Biliary adenoma is uncommon benign neoplasm of the biliary system

of unknown aetiology and account for approximately 0.1%-2% of all gastrointestinal benign tumors. Most of patients are asymptomatic; a few patients have mild jaundice or abdominal discomfort. To our knowledge

there were only a few cases of biliary papillomatosis reported in the previous literatures

which only showed solitary tumor in bile duct. We presented a rare case with multiple biliary adenomas in extrahepatic bile duct confirmed by endoscopic retrograde cholangiopancreatography（ERCP） and histopathology. After 3 months follow-up

the patient remained asymptomatic.